U.S. flag

An official website of the United States government

Format

Send to:

Choose Destination

Von Voss-Cherstvoy syndrome

MedGen UID:
341728
Concept ID:
C1857226
Disease or Syndrome
Synonyms: DK phocomelia syndrome; Phocomelia thrombocytopenia encephalocele and urogenital malformations; PHOCOMELIA, THROMBOCYTOPENIA, ENCEPHALOCELE, UROGENITAL MALFORMATIONS
SNOMED CT: DK phocomelia syndrome (719021005); Von Voss-Cherstvoy syndrome (719021005); Phocomelia, thrombocytopenia, encephalocele and urogenital malformation syndrome (719021005)
Modes of inheritance:
Autosomal recessive inheritance
MedGen UID:
141025
Concept ID:
C0441748
Intellectual Product
Source: Orphanet
A mode of inheritance that is observed for traits related to a gene encoded on one of the autosomes (i.e., the human chromosomes 1-22) in which a trait manifests in individuals with two pathogenic alleles, either homozygotes (two copies of the same mutant allele) or compound heterozygotes (whereby each copy of a gene has a distinct mutant allele).
 
Monarch Initiative: MONDO:0009121
OMIM®: 223340
Orphanet: ORPHA3439

Definition

A very rare disorder with phocomelia of upper limbs, encephalocele, variable brain anomalies, urogenital abnormalities and thrombocytopenia. Less than 15 cases have been reported. The spectrum of upper limb defects varies from radial agenesis and phocomelia to amelia. A meningoencephalocele is constant. The intellectual development may be normal. Pathogenesis and cause of this syndrome are unknown. Parental consanguinity reported in a family suggests an autosomal recessive pattern of inheritance. [from SNOMEDCT_US]

Clinical features

From HPO
Abnormality of the genitourinary system
MedGen UID:
52948
Concept ID:
C0042063
Congenital Abnormality
The presence of any abnormality of the genitourinary system.
Encephalocele
MedGen UID:
1646412
Concept ID:
C4551722
Congenital Abnormality
A neural tube defect characterized by sac-like protrusions of the brain and the membranes that cover it through openings in the skull.
Thrombocytopenia
MedGen UID:
52737
Concept ID:
C0040034
Disease or Syndrome
A reduction in the number of circulating thrombocytes.
Phocomelia
MedGen UID:
10721
Concept ID:
C0031575
Congenital Abnormality
Missing or malformed long bones of the extremities with the distal parts (such as hands and/or feet) connected to the variably shortened or even absent extremity, leading to a flipper-like appearance, as opposed to other forms of limb malformations were either the hole limb is missing (such as amelia), or the distal part of a limb is absent (peromelia).

Term Hierarchy

CClinical test,  RResearch test,  OOMIM,  GGeneReviews,  VClinVar  
  • CROGVVon Voss-Cherstvoy syndrome
Follow this link to review classifications for Von Voss-Cherstvoy syndrome in Orphanet.

Recent clinical studies

Etiology

Chen CP
Taiwan J Obstet Gynecol 2008 Sep;47(3):276-82. doi: 10.1016/S1028-4559(08)60124-2. PMID: 18935989
Lubinsky MS, Kahler SG, Speer IE, Hoyme HE, Kirillova IA, Lurie IW
Am J Med Genet 1994 Sep 1;52(3):272-8. doi: 10.1002/ajmg.1320520305. PMID: 7810558

Diagnosis

Chen CP
Taiwan J Obstet Gynecol 2008 Sep;47(3):276-82. doi: 10.1016/S1028-4559(08)60124-2. PMID: 18935989
Managoli S, Chaturvedi P, Vilhekar KY, Kumar S
Indian Pediatr 2002 Oct;39(10):967-9. PMID: 12428045

Prognosis

Chen CP
Taiwan J Obstet Gynecol 2008 Sep;47(3):276-82. doi: 10.1016/S1028-4559(08)60124-2. PMID: 18935989
Managoli S, Chaturvedi P, Vilhekar KY, Kumar S
Indian Pediatr 2002 Oct;39(10):967-9. PMID: 12428045

Clinical prediction guides

Brunetti-Pierri N, Mendoza-Londono R, Shah MR, Karaviti L, Lee B
Am J Med Genet A 2004 Apr 30;126A(3):299-302. doi: 10.1002/ajmg.a.20593. PMID: 15054846

Supplemental Content

Recent activity

Your browsing activity is empty.

Activity recording is turned off.

Turn recording back on

See more...